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Temporal lobe epilepsy manifests refractory recurrent abdominal visceral pain in a 7-year-old children

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机构: [1]Capital Med Univ, Beijing Inst Brain Disorders, Beijing, Peoples R China [2]Capital Med Univ, Xuanwu Hosp, Beijing Inst Funct Neurosurg, Beijing, Peoples R China [3]Univ British Columbia, Djavad Mowafaghian Ctr Brain Hlth, Vancouver, BC, Canada [4]BC Benefit Co, NeuroPrior INC, Vancouver, BC, Canada
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关键词: Refractory visceral pain Temporal lobe epilepsy Amygdala Anterior temporal lobectomy

摘要:
Refractory Recurrent abdominal visceral pain (RAVP) is a severe condition and can be difficult to diagnose and manage due to its poorly understood pathophysiological mechanisms. Here we re-port a 7-year-old patient with a 2-year history of temporal lobe epilepsy manifesting refractory RAVP. The patient was treated with anterior temporal lobectomy (including the amygdala and the hippocampal formation), and the pain resolved completely after surgery. The patient re-mained free of seizures and pain during 4 years of post-surgery follow-up. Based on this case and previous studies, we speculate a central mechanism and neuromodulation target for refractory visceral pain.

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大类 | 4 区 医学
小类 | 4 区 儿科
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Q4 PEDIATRICS

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第一作者机构: [1]Capital Med Univ, Beijing Inst Brain Disorders, Beijing, Peoples R China [2]Capital Med Univ, Xuanwu Hosp, Beijing Inst Funct Neurosurg, Beijing, Peoples R China [3]Univ British Columbia, Djavad Mowafaghian Ctr Brain Hlth, Vancouver, BC, Canada [4]BC Benefit Co, NeuroPrior INC, Vancouver, BC, Canada
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通讯机构: [1]Capital Med Univ, Beijing Inst Brain Disorders, Beijing, Peoples R China [2]Capital Med Univ, Xuanwu Hosp, Beijing Inst Funct Neurosurg, Beijing, Peoples R China [3]Univ British Columbia, Djavad Mowafaghian Ctr Brain Hlth, Vancouver, BC, Canada [4]BC Benefit Co, NeuroPrior INC, Vancouver, BC, Canada [*1]Djavad Mowafaghian Centre for Brain Health, University of British Columbia, Vancouver, British Columbia, Canada.
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